Chediak-Higashi syndrome: report of a case with uncommon presentation and review literature.

نویسنده

  • Somjai Kanjanapongkul
چکیده

Chediak-Higashi syndrome (CHS) is a very rare autosomal recessive immunodeficiency disorder characterized by partial albinism, recurrent pyogenic infections, and large granules in all granule-containing cells. The author describes a Thai girl who was the first case of CHS in Thailand. She presented in the accelerated phase of CHS, which leads to repeated infections and bleeding, often resulting in fatal outcome. Pancytopenias, hepatosplenomegaly, lymphohistiocytic infiltration in bone marrow and the abnormal characteristic granules in leukocyte clinched the diagnosis.

برای دانلود متن کامل این مقاله و بیش از 32 میلیون مقاله دیگر ابتدا ثبت نام کنید

ثبت نام

اگر عضو سایت هستید لطفا وارد حساب کاربری خود شوید

منابع مشابه

Chediak-Higashi Syndrome: A case report

Introduction: Chediak-Higashi syndrome is a rare autosomal recessive disorder that characterized by severe immunodeficiency. It is also associated with a lymphoproliferative disorder termed the accelerated phase with lymphocytic infiltration of the major organ of the body. Case Report: The patients was a 1-year old boy with intermittent fever, anorexia, malaise. On physical examination h...

متن کامل

Acute promyelocytic leukemia with pseudo-Chediak-Higashi anomaly: a case report and review of the literature.

The hypergranular type of acute promyelocytic leukemia (APL) is characterized by heavy granulation and the presence of Auer rods. These granules are usually small, azurophilic, and have the appearance of the primary granules of normal promyelocytes. There have been several reports of myeloid leukemias, including APL, with the unusual finding of large granules (inclusions) simulating the inclusi...

متن کامل

Elejalde syndrome: report of a case and review of the literature.

Elejalde syndrome is a rare autosomal recessive condition, with only 10 reported cases through 2001. It is characterized by silvery hair, pigment abnormalities, and profound central nervous system dysfunction. The differential diagnosis includes Griscelli and Chediak-Higashi syndromes, which present with silvery hair, pigment abnormalities, central nervous system alterations, and severe immunol...

متن کامل

Intradural Lumbar Disc Herniation: Report of Two Cases and Review of the Literature

Background and Importance: Intradural lumbar disc herniation is a rare and uncommon presentation of lumbar disc herniation. It signifies a challenge for diagnostic and therapeutic scheme, and is associated with a greater incidence of cauda equina syndrome at presentation. Case Presentation: We describe two cases of intradural disc herniation who underwent surgery in Senegal review literat...

متن کامل

May-Thurner syndrome, an uncommon diagnosis for a common disease: a case report and review of the literature

May-Turner syndrome is a relatively uncommon anatomical variation in which patients develop iliofemoral deep vein thrombosis (DVT) due to venous occlusion. In this syndrome, the left common iliac vein is compressed against the fifth lumbar vertebra by the right common iliac artery. The real incidence/prevalence of May-Turner syndrome is not precisely known, but it is estimated to be between 22 ...

متن کامل

ذخیره در منابع من


  با ذخیره ی این منبع در منابع من، دسترسی به آن را برای استفاده های بعدی آسان تر کنید

برای دانلود متن کامل این مقاله و بیش از 32 میلیون مقاله دیگر ابتدا ثبت نام کنید

ثبت نام

اگر عضو سایت هستید لطفا وارد حساب کاربری خود شوید

عنوان ژورنال:
  • Journal of the Medical Association of Thailand = Chotmaihet thangphaet

دوره 89 4  شماره 

صفحات  -

تاریخ انتشار 2006